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Article

Harmonin (Ush1c) is required in zebrafish Müller glial cells for photoreceptor synaptic development and function.

Disease models & mechanisms - 1 Nov 2011

Phillips Jennifer B, Blanco-Sanchez Bernardo, Lentz Jennifer J, Tallafuss Alexandra, Khanobdee Kornnika, Sampath Srirangan, Jacobs Zachary G, Han Philip F, Mishra Monalisa, Titus Tom A, Williams David S, Keats Bronya J, Washbourne Philip, Westerfield Monte

Abstract excerpt

Usher syndrome is the most prevalent cause of hereditary deaf-blindness, characterized by congenital sensorineural hearing impairment and progressive photoreceptor degeneration beginning in childhood or adolescence. Diagnosis and management of this disease are complex, and the molecular changes underlying sensory cell impairment remain poorly understood. Here we characterize two zebrafish models for a severe form...

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Methodology Data sources Editorial policy Privacy About Contact Helena Bioinformatics

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Identifiers

PMID: 21757509
DOI: 10.1242/dmm.006429
PMCID: PMC3209648

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PubMed metadata and Literature Corpus relationships. Corpus snapshot updated 7 Sept 2026. Manifest publication-graph-cohort-2026-09-07.1.

Source receipt: pubmed, retrieved 7 Sept 2026.

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Harmonin (Ush1c) is required in zebrafish Müller glial cells for photoreceptor synaptic development and function.PMID 21757509Read ↗

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